Abnormal morphology of fibrillin microfibrils in fibroblast cultures from patients with neonatal Marfan syndrome.

Details

Serval ID
serval:BIB_936B9898579F
Type
Article: article from journal or magazin.
Collection
Publications
Title
Abnormal morphology of fibrillin microfibrils in fibroblast cultures from patients with neonatal Marfan syndrome.
Journal
American Journal of Pathology
Author(s)
Godfrey M., Raghunath M., Cisler J., Bevins C.L., DePaepe A., Di Rocco M., Gregoritch J., Imaizumi K., Kaplan P., Kuroki Y., Silberbach M., Supertifurga A., Vanthienen M.N., Vetter U., Steinmann B.
ISSN
0002-9440 (Print)
ISSN-L
0002-9440
Publication state
Published
Issued date
1995
Volume
146
Number
6
Pages
1414-1421
Language
english
Notes
Publication types: Journal Article ; Research Support, Non-U.S. Gov't ; Research Support, U.S. Gov't, P.H.S.
Abstract
The Marfan syndrome (MFS) is a connective tissue disorder manifested by variable and pleiotropic features in the skeletal, ocular, and cardiovascular systems. The average life span in MFS is about 35 years. A group with much more severe cardiovascular disease and a mean life span of approximately 1 year also exists. We refer to this latter group as "neonatal Marfan syndrome" (nMFS). Fibrillin defects are now known to be the cause of MFS and nMFS. Immunofluorescence studies were the first to demonstrate this association. Here we describe immunofluorescence studies in a series of 10 neonates and summarize their salient clinical features. In vitro accumulation of fibrillin reactive fibers was assayed using monoclonal antibodies to fibrillin in hyperconfluent fibroblast cultures. As was previously observed in MFS, fibroblast cultures from nMFS patients showed an apparent decrease in accumulation of immunostainable fibrillin. Significantly, however, the morphology of the immunostained fibrils in the nMFS cultures were abnormal and differed not only from control cultures, but also from those seen in cultures of MFS fibroblasts. The nMFS fibrils appeared short, fragmented, and frayed, characteristics that are not seen in MFS. Both the clinical and fibrillin morphology data provide evidence to suggest a useful subclassification of nMFS in the spectrum of MFS.
Keywords
Cells, Cultured, Child, Child, Preschool, Connective Tissue/chemistry, Extracellular Matrix Proteins/analysis, Extracellular Matrix Proteins/ultrastructure, Female, Fibroblasts, Fluorescent Antibody Technique, Humans, Infant, Newborn, Male, Marfan Syndrome/classification, Marfan Syndrome/pathology, Microfilament Proteins/analysis, Microfilament Proteins/ultrastructure
Pubmed
Web of science
Create date
14/03/2011 17:14
Last modification date
20/08/2019 15:56
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