Esophageal leiomyoma in children: two case reports and review of the literature

Détails

ID Serval
serval:BIB_1CA0B99BA9C9
Type
Article: article d'un périodique ou d'un magazine.
Sous-type
Etude de cas (case report): rapporte une observation et la commente brièvement.
Collection
Publications
Titre
Esophageal leiomyoma in children: two case reports and review of the literature
Périodique
Journal of Pediatric Surgery
Auteur(s)
Bourque  M. D., Spigland  N., Bensoussan  A. L., Collin  P. P., Saguem  M. H., Brochu  P., Blanchard  H., Reinberg  O.
ISSN
0022-3468 (Print)
Statut éditorial
Publié
Date de publication
10/1989
Volume
24
Numéro
10
Pages
1103-7
Notes
Case Reports
Journal Article
Review --- Old month value: Oct
Résumé
Leiomyoma of the esophagus is not uncommon in the adult population but is rarely seen in children; only 20 cases have been reported in the pediatric population. In this paper we describe two cases of esophageal leiomyoma in female patients aged 6 and 13 years and review previous reports. Several differences were noted between the pediatric and adult population. The mean age in children is 14 years (range, 4 to 20 years). Leiomyoma appears 1.71 times more often in females than in males. Localized lesions are found in only 9%, whereas the diffuse form predominates in 91%. The entire esophagus may be involved 35% of the time, and encroachment on the cardia or upper stomach occurs in 70%. Leiomyomas associated with familial syndromes (familial leiomyoma and Alport's syndrome) occur in 22% of the cases. Major symptoms include dysphagia (86%), dyspnea (36%), vomiting (27%), retrosternal pain (27%), and coughing (22%). The initial diagnosis following contrast studies is most often achalasia. The diagnosis of leiomyoma is made only with subsequent endoscopy. Enucleation was performed in only 11% of the cases; surgical resection (including part of the stomach) was necessary in 78% with a 21% postoperative mortality. Esophageal leiomyoma should be considered in the differential diagnosis of mediastinal masses and esophageal obstruction. Accurate preoperative diagnosis is desirable in order to plan proper surgical treatment.
Mots-clé
Adolescent Child Esophageal Neoplasms/diagnosis/*surgery Female Humans Leiomyoma/diagnosis/*surgery
Pubmed
Web of science
Création de la notice
28/01/2008 10:12
Dernière modification de la notice
03/03/2018 14:32
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