A facial inflammatory myofibroblastic tumour in a 6-year-old girl: plastic surgery lessons from a rare case.

Details

Serval ID
serval:BIB_3EB227832E37
Type
Article: article from journal or magazin.
Publication sub-type
Case report (case report): feedback on an observation with a short commentary.
Collection
Publications
Title
A facial inflammatory myofibroblastic tumour in a 6-year-old girl: plastic surgery lessons from a rare case.
Journal
Journal of cranio-maxillo-facial surgery
Author(s)
Modarressi A., Pietramaggiori G., Bezzola T., Lacroix S., Richter M., Rilliet B., Pittet B.
ISSN
1878-4119 (Electronic)
ISSN-L
1010-5182
Publication state
Published
Issued date
03/2011
Peer-reviewed
Oui
Volume
39
Number
2
Pages
141-144
Language
english
Notes
Publication types: Case Reports ; Journal Article ; Review
Publication Status: ppublish
Abstract
Inflammatory myofibroblastic tumours (IMT) are rare, challenging lesions with respect to differential diagnosis, biological behaviour and treatment. We reviewed the literature and report a unique case of a large (9 × 8 × 8 cm) IMT in the nasal region of a 6-year-old girl responsible for important facial deformation. Following surgical resection, without any craniofacial reconstruction, the dysmorphism regressed spontaneously with a good result at 2 years of follow-up. To date, this is the largest IMT reported. Surprisingly, after simple excision of the tumour the craniofacial bones and soft tissues regained spontaneously their normal anatomical position only after a few months. The bone plasticity was likely due to the young age of patient and the preservation of periosteum and muscles during the surgical excision. We conclude that a conservative approach may be considered as alternative to reconstructive surgery in particular cases in young subjects.

Keywords
Bone Regeneration, Child, Facial Bones/growth & development, Facial Neoplasms/diagnostic imaging, Facial Neoplasms/pathology, Facial Neoplasms/surgery, Female, Granuloma, Plasma Cell/diagnostic imaging, Granuloma, Plasma Cell/pathology, Granuloma, Plasma Cell/surgery, Humans, Myofibroblasts/pathology, Neoplasm Recurrence, Local/diagnostic imaging, Neoplasm Recurrence, Local/surgery, Neoplasms, Muscle Tissue/diagnostic imaging, Neoplasms, Muscle Tissue/pathology, Neoplasms, Muscle Tissue/surgery, Radiography, Treatment Outcome
Pubmed
Web of science
Create date
16/01/2018 14:25
Last modification date
20/08/2019 13:35
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